Unilateral congenital nasal pyriform aperture stenosis and unilateral choanal atresia – a novel finding: A case report
DOI:
https://doi.org/10.7196/SAMJ.2022.v112i11b.16839Keywords:
Stenosis, NasalAbstract
Congenital nasal pyriform aperture stenosis (CNPAS) is a rare cause of upper airway obstruction in infants, with an incidence of 1 in
25 000 live births. Choanal atresia (CA) is a more common cause of upper airway obstruction, with an incidence of 1 in 5 000 - 8 000 live
births. These two conditions often occur independently of each other. Radiologists frequently misinterpret CNPAS as CA. We present a
case in which unilateral CNPAS and unilateral CA occurred in the same patient on opposite sides of the nose. The patient had none of
the associated craniofacial abnormalities or syndromes. The CNPAS was successfully treated with a sub-labial approach and drilling of the stenotic pyriform aperture, while the CA was dilated with Lister dilators.
References
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Angulo C, Jayawardena ADL, Caruso PA, et al. Congenital nasal piriform aperture atresia: A case report and novel finding. Int J Pediatr Otorhinolaryngol 2020;135:110124. https://doi.org/10.1016/j. ijporl.2020.110124
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